Conserved Sequence Motifs in Immunoglobulin Loci
Potential Role for Hypermutation Recruitment

Background:
Betz, 1994. Elements regulating somatic hypermutation of an immunoglobulin kappa gene: critical role for the intron enhancer/matrix attachment region. (Milstein lab)
Conclusion: The VDJ promoter was replaced with an Hb promoter, and it was found that hypermutation was unaffected in  kappa TG. Therefore, the promoter does not specifically target hypermutation.

Yelamos, 1995. Targeting of non-Ig sequences in place of the V segment by somatic hypermutation. (Milstein/Neuberger lab)
Conclusion: The V gene sequences do not recruit somatic hypermutation to the VDJ region, as mutations were found in the beta globin gene when it replaced the V gene in the Ig kappa transgene.

Lin, 1998. (Scharff lab) The effects of E mu, 3’ alpha and 3’ kappa enhancers on mutation of an Ig-VDJ-Cgamma2a Ig heavy gene in cultured B cells
Conclusion: The intronic enhancer was replaced with an SV40 or CMV enhancer region, in both orientations. The hypermutation frequency was unaffected, but the transcription was 4 – 20 times lower than with the endogenous Ei. The addition of the 3’ kappa or 3’ alpha enhancer regions did not increase the frequency of hypermutation.

Kenny, 2001. Mutational analysis of immunoglobulin germline-derived vlambda4b light chains in rheumatoid arthritis. .
Conclusion: Lambda chains also undergo hypermutation.

Bachl, 2001. Increased transcription levels induce higher mutation rates in a hypermutating cell line.
Conclusion: The rate of transcription correlate directly with the rate of hypermutation. AID is transcribed in the hypermutating cell line.

Summary:
The rearranged Ig genes in both the IgH and the IgL loci undergo somatic hypermutation in activated B cells following stimulation with antigen. The hypermutating region starts at the promoter, and continues downstream for about 2 kB. Transcription of the gene is essential for hypermutation. Rate of transcription is correlated with the rate of hypermutation. There are several promoters found in the Ig loci: kappa Ei, 3’E kappa, E lambda, heavy Ei, 3’ E alpha. The enhancers are essential for hypermutation, however, if they are replaced with viral enhancers, hypermutation still occurs. Likewise, the promoter is also essential, but can be replaced. The identity of the gene that is being hypermutated is also irrelevant. Activation-induced cytosine deaminase (AID) is essential for both somatic hypermutation as well as switch recombination. This implies that similar mechanisms are at play in the two phenomena. However, switch recombination occurs independently of hypermutation, and vice versa.

The plan:
 It seems that a consensus sequence for recruiting hypermutation should exist, but it has not been found yet. However, the above experiments have ruled out certain regions:
a. The promoter and the actual gene.
b. The Ei and the MARs on the heavy chain. The experiments in the IgH have not been repeated in the IgL loci, so it is not certain that the kappa and lambda promoters do not participate in hypermutation recruitment.
c. The 3’E alpha promoter is an interesting conundrum. The transgene that was tested for hypermutation did not contain the 3’ alpha enhancer. In the endogenous IgH locus, the 3’Ea is around 200 kB from the V(D)J. Could this element act over 200 kB, or perhaps even across chromosomes? It is unlikely. Indeed, if it did act across chromosomes, it’s unlikely that the 3’Ea confers specificity to recruit hypermutation. Thus, this also can’t be the hypermutation consensus sequence (HCS).

With the above taken into account, there are several possible locations for the HCS in the IgH and IgL kappa loci:
1. 3’ of J and 5’ of the Ei region. However, Klix (1998) made an IgL kappa transgene where 1.07 kB of this region was deleted. A normal rate of mutation was found in this transgene. Another thing to consider is that this region still undergoes hypermutation. Thus, it would not be the ideal place for a conserved sequence.
2. 3’ of Ei and 5’ of the switch region in IgH r 5’ of Ck in Ig kappa. In the same kappa transgene, Klix had also deleted 0.43 kB of this region, leaving a very small amount of sequence. Thus, it’s once again unlikely that this region contains the HCS, but it should still be investigated.
3. 3’ of switch region and 3’ of C. This is a very large region (up to 60kB in IgG3). However, this region is also present in every constant region. There are 11 constant regions in the human IgH. These can all be compared for conserved pattern motifs.

The experiment:
1. Obtain the following sequences of IgH (and alter for IgL):
a. 3’ of J to 5’ of C.
b. 3’ of C to 5’ of the next C.
2. Divide the a) sequence into the following segments:
1. 3’ of J to 5’ of Ei/MAR
2. 3’ of Ei/MAR to 5’ of the switch region.
3. 3’ of switch to 5’ of C.
3. Compare the sequence chunks. i.e. all the ‘3 J to 5’ Ei/MAR should be compared to each other, etc. Isolate conserved sequence motifs.
4. If one of the samples doesn’t contain the conserved sequence, look for the sequence in the other parts of that sample.
5. To compare, use: Teiresias, MACAW, Gibbs. Also ompare IgH and IgL.
6. Later, try TUNA.

Positive control
There is no known HCS, but the HCS must have the following properties:
1. It must be present in all the genes that undergo hypermutation, IH, Igkappa and Iglambda.
2. It should be fairly conserved.
3. A protein should bind to the HCS.
4. When it is deleted, no hypermutation should occur.
1 and 2 can be tested by bioinformatics, but 3 is for the wet lab, and a cell line-transgene experiments, with the 18.8 or NSO cell line.

Negative control
It is difficult to have an absolute negative control, as the hypermutation machinery might use a specific combination of proteins. Some of the individual proteins might be found in other tissues, but the specific combination is not. Thus, the key for the negative control lies in selecting a gene that has many of the similar regulatory elements as the Ig, is expressed at the same time as the Ig, but does not hypermutate.

I believe that an excellent choice for the negative control gene is the Ig beta gene. It is expressed in B cells, and it is transcribed during the period hypermutation occurs. It is also under the control of many of the same regulatory elements as the IgH and IgL genes. However, it does not hypermutate. Thus, it should not ontain the HCS.

Another possibility is the TcR gene. These undergo recombination, but not somatic hypermutation. However, they are expressed in T cells, and not B cells. In B cells, they are in the unrearranged form, so hypermutation would not ccur even if the HCS was present. Nonetheless, from the looks of it, the somatic hypermutation and switch recombination are quite unique to the B cells, so might it be that the HCS is also unique? This gene will serve as an interesting quasi-negative control.

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